Search results for " multiple"

showing 10 items of 903 documents

Clinical Delineation Of A Subtype Of Frontonasal Dysplasia With Creased Nasal Ridge And Upper Limb Anomalies: Report Of Six Unrelated Patients

2017

IF 2.259; International audience; Frontonasal dysplasias are rare congenital malformations of frontonasal process-derived structures, characterized by median cleft, nasal anomalies, widely spaced eyes, and cranium bifidum occultum. Several entities of syndromic frontonasal dysplasia have been described, among which, to date, only a few have identified molecular bases. We clinically ascertained a cohort of 124 individuals referred for frontonasal dysplasia. We identified six individuals with a similar phenotype, including one discordant monozygous twin. Facial features were remarkable by nasal deformity with creased ridge and depressed or absent tip, widely spaced eyes, almond-shaped palpebr…

Heart Defects CongenitalMale0301 basic medicineChoanal atresiaNoseBiologyfrontonasal dysplasiaChoanal AtresiaFacial BonesEncephaloceleCohort StudiesCraniofacial Abnormalities03 medical and health sciences0302 clinical medicineExome SequencingGeneticsmedicineHumansAbnormalities MultipleFrontonasal dysplasia[ SDV.GEN.GH ] Life Sciences [q-bio]/Genetics/Human geneticsGenetics (clinical)Exome sequencingEncephalocelenasofrontal encephaloceleCorpus Callosum AgenesisInfantAnatomymedicine.diseasePhenotype030104 developmental biologyPalpebral fissuremedicine.anatomical_structure[SDV.GEN.GH]Life Sciences [q-bio]/Genetics/Human geneticsnasal malformationFaceEtiologyUpper limbFemaleAgenesis of Corpus Callosum030217 neurology & neurosurgery
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Genetic syndrome suspicion: examples of clinical approach in the neonatal unit.

2010

Overgrowth syndromes: the practical clinical approach. Excessive growth can be present in a variety of medical conditions as result of abnormal fetal metabolism (i.e., maternal gestational diabetes) or of an overgrowth syndrome. Within this latter group of diseases, a LGA newborn requires a complex differential diagnosis encompassing several syndromes, such as Beckwith-Wiedemman, Sotos, Weaver, Simpson-Golabi-Behmel, Perlman, and Bannayan-Riley-Ruvalcaba. Partial or global overgrowth, other dysmorphisms, abdominal organs anomalies, as well as benign and malignant tumors are the common issues to examine for the diagnosis and the monitoring of all these disorders. The molecular bases of these…

Heart Defects CongenitalPatient Care Teamgenetic syndromesGenetic Diseases InbornInfant NewbornLimb Deformities CongenitalAnal CanalSyndromeKidneySpineCongenital AbnormalitiesFetal MacrosomiaTracheaEarly DiagnosisEsophagusSettore MED/38 - Pediatria Generale E SpecialisticaIntensive Care Units NeonatalBirth WeightHumansAbnormalities MultipleHedgehog ProteinsGenetic TestingNeonatologyEsophageal Atresiasyndrome genetic
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Perlecan Maintains the Integrity of Cartilage and Some Basement Membranes

1999

Perlecan is a heparan sulfate proteoglycan that is expressed in all basement membranes (BMs), in cartilage, and several other mesenchymal tissues during development. Perlecan binds growth factors and interacts with various extracellular matrix proteins and cell adhesion molecules. Homozygous mice with a null mutation in the perlecan gene exhibit normal formation of BMs. However, BMs deteriorate in regions with increased mechanical stress such as the contracting myocardium and the expanding brain vesicles showing that perlecan is crucial for maintaining BM integrity. As a consequence, small clefts are formed in the cardiac muscle leading to blood leakage into the pericardial cavity and an ar…

Heart Defects Congenitalcardiac muscleMesenchymeSchwartz–Jampel syndromeRestriction MappingPerlecanBasement MembraneExtracellular matrixMiceMice CongenicchondrodysplasiaCalcification PhysiologicexencephalyLamininmedicineAnimalsNeural Tube DefectsCells CulturedBasement membranebiologyCartilageOssification HeterotopicHomozygoteCell Biologymedicine.diseaseMice Mutant StrainsBasement membrane assemblyCell biologyperlecanMutagenesis Insertionalmedicine.anatomical_structureCartilageBiochemistryGene Targetingbiology.proteinOriginal ArticleGenes LethalProteoglycansCollagenHeparitin SulfateExostoses Multiple HereditaryHeparan Sulfate ProteoglycansThe Journal of Cell Biology
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Hematopoietic Stem Cell Transplantation in People With Active Secondary Progressive Multiple Sclerosis

2023

Background and ObjectivesUncontrolled evidence suggests that autologous hematopoietic stem cell transplantation (AHSCT) can be effective in people with active secondary progressive multiple sclerosis (SPMS). In this study, we compared the effect of AHSCT with that of other anti-inflammatory disease-modifying therapies (DMTs) on long-term disability worsening in active SPMS.MethodsWe collected data from the Italian Bone Marrow Transplantation Study Group and the Italian Multiple Sclerosis Register. Patients were considered eligible if treatment had been started after the diagnosis of SPMS. Disability worsening was assessed by the cumulative proportion of patients with a 6-month confirmed dis…

Hematopoietic Stem Cell TransplantationActive Secondary Progressive Multiple SclerosisNeurology (clinical)Research Article
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Immunohistochemical Study as a Tool in Differential Diagnosis of Pediatric Malignant Rhabdoid Tumor

2010

Malignant rhabdoid tumors (MRTs) are aggressive childhood neoplasms, occurring mainly in the kidney and brain. We describe 2 unusual cases of extrarenal and noncranial location (liver and soft tissue with dissemination) mimicking hepatoblastoma, neuroblastoma or Ewing sarcoma. Both cases revealed a polyphenotypic profile, combined with cytokeratin, vimentin, and CD99 expression. INI1/BAF-47 showed negative protein nuclear expression in both cases, suggesting a diagnosis of MRT. An extensive immunohistochemical panel was performed to exclude pediatric tumors reminiscent of MRT. The genetic studies failed to detected MYCN amplification, 11q23 deletion, and EWS break-apart positivity. No alter…

HepatoblastomaPathologymedicine.medical_specialtySkin NeoplasmsHistologyDesmoplastic small-round-cell tumorChromosomal Proteins Non-HistoneCD9912E7 AntigenN-Myc Proto-Oncogene ProteinPathology and Forensic MedicineDiagnosis DifferentialNeoplasms Multiple PrimaryFatal OutcomeAntigens CDNeuroblastomaAntineoplastic Combined Chemotherapy ProtocolsmedicineHumansVimentinRhabdoid TumorChromosome AberrationsOncogene ProteinsN-Myc Proto-Oncogene Proteinbusiness.industryLiver NeoplasmsInfant NewbornInfantNuclear ProteinsWilms' tumorSMARCB1 Proteinmedicine.diseaseImmunohistochemistryDNA-Binding ProteinsMedical Laboratory TechnologyDrug Resistance NeoplasmKeratinsFemaleSarcomaRNA-Binding Protein EWSDifferential diagnosisbusinessCell Adhesion MoleculesTranscription FactorsApplied Immunohistochemistry & Molecular Morphology
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Multiplex ligation-dependent probe amplification detection of an unknown large deletion of the CREB-binding protein gene in a patient with Rubinstein…

2013

Rubinstein-Taybi syndrome is a rare autosomal dominant congenital disorder characterized by postnatal growth retardation, psychomotor developmental delay, skeletal anomalies, peculiar facial morphology, and tumorigenesis. Mutations in the gene encoding the cAMP response element-binding protein (CREB, also known as CREBBP or CBP) on chromosome 16p13.3 have been identified. In addition, some patients with low intelligence quotients and autistic features bear large deletions. Based on these observations, we used multiplex ligation-dependent probe amplification to search for large deletions affecting the CREBBP gene in a Rubinstein-Taybi syndrome patient. We identified a novel heterozygote dele…

HeterozygoteCREBExonSettore BIO/13 - Biologia ApplicataGeneticsmedicineHumansMultiplexMultiplex ligation-dependent probe amplificationGenetic TestingCREB-binding proteinMolecular BiologyGeneGeneticsRubinstein-Taybi SyndromeRubinstein–Taybi syndromebiologyMultiplex ligation-dependent probe amplification Comparative multiplex dosage analysis CREB-binding protein Rubinstein-Taybi syndromeHeterozygote advantageGeneral Medicinemedicine.diseaseMolecular biologyCREB-Binding ProteinChild Preschoolbiology.proteinFemaleMultiplex Polymerase Chain ReactionGene Deletion
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Adaptive Collision Avoidance through Implicit Acknowledgments in WSNs

2008

The large number of nodes, typical of many sensor network deployments, and the well-known hidden terminal problem make collision avoidance an essential goal for the actual employment of WSN technology. Collision avoidance is traditionally dealt with at the MAC Layer and plenty of different solutions have been proposed, which however have encountered limited diffusion because of their incompatibility with commonly available devices.In this paper we propose an approach to collision avoidance which is designed to work over a standard MAC Layer, namely the IEEE 802.15.4 MAC, and is based on application-controlled delays of packet transmission times. The proposed scheme is simple, decentralized …

Hidden node problemComputer sciencebusiness.industryComputerSystemsOrganization_COMPUTER-COMMUNICATIONNETWORKSSynchronizationTree (data structure)ScalabilityMultiple Access with Collision Avoidance for WirelessWireless Sensor NetworksbusinessWireless sensor networkCollision avoidanceCarrier sense multiple access with collision avoidanceComputer network2008 IEEE Asia-Pacific Services Computing Conference
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Revisit of RTS/CTS Exchange in High-Speed IEEE 802.11 Networks

2005

IEEE 802.11 medium access control (MAC), called distributed coordination function (DCF), provides two different access modes, namely, 2-way (basic access) and 4-way (RTS/CTS) handshaking. The 4-way handshaking has been introduced in order to combat the hidden terminal phenomenon. It has been also proved that such a mechanism can be beneficial even in the absence of hidden terminals, because of the collision time reduction. We analyze the effectiveness of the RTS/CTS access mode, in current 802.11b and 802.11a networks. Since the rates employed for control frame transmissions can be much lower than the rate employed for data frames, the assumption on the basis of the 4-way handshaking introd…

Hidden node problembusiness.industryComputer scienceReal-time computingFrame (networking)Wireless local area networks (WLAN)Distributed coordination functionThroughputbackoff algorithmHandshakingMedia access controlMultiple Access with Collision Avoidance for WirelessIEEE 802.11e-2005businessCarrier sense multiple access with collision avoidanceComputer networkSixth IEEE International Symposium on a World of Wireless Mobile and Multimedia Networks
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Cytotoxicity of the bisphenolic honokiol from Magnolia officinalis against multiple drug-resistant tumor cells as determined by pharmacogenomics and …

2014

A main problem in oncology is the development of drug-resistance. Some plant-derived lignans are established in cancer therapy, e.g. the semisynthetic epipodophyllotoxins etoposide and teniposide. Their activity is, unfortunately, hampered by the ATP-binding cassette (ABC) efflux transporter, P-glycoprotein. Here, we investigated the bisphenolic honokiol derived from Magnolia officinalis. P-glycoprotein-overexpressing CEM/ADR5000 cells were not cross-resistant to honokiol, but MDA-MB-231 BRCP cells transfected with another ABC-transporter, BCRP, revealed 3-fold resistance. Further drug resistance mechanisms analyzed study was the tumor suppressor TP53 and the epidermal growth factor recepto…

HonokiolATP Binding Cassette Transporter Subfamily BPharmaceutical ScienceBiologyPharmacologyLignanschemistry.chemical_compoundGefitinibCell Line TumorDrug DiscoverymedicineATP Binding Cassette Transporter Subfamily G Member 2HumansEpidermal growth factor receptorCytotoxicityPI3K/AKT/mTOR pathwayOligonucleotide Array Sequence AnalysisPharmacologyBiphenyl CompoundsTransfectionbiology.organism_classificationAntineoplastic Agents PhytogenicDrug Resistance MultipleNeoplasm ProteinsErbB ReceptorsMolecular Docking SimulationMagnolia officinalisComplementary and alternative medicinechemistryDrug Resistance NeoplasmMagnoliaPharmacogeneticsbiology.proteinMolecular MedicineATP-Binding Cassette TransportersErlotinibTumor Suppressor Protein p53Transcriptomemedicine.drugSignal TransductionPhytomedicine : international journal of phytotherapy and phytopharmacology
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New efficient artemisinin derived agents against human leukemia cells, human cytomegalovirus and Plasmodium falciparum: 2nd generation 1,2,4-trioxane…

2015

Abstract In our ongoing search for highly active hybrid molecules exceeding their parent compounds in anticancer, antimalaria as well as antiviral activity and being an alternative to the standard drugs, we present the synthesis and biological investigations of 2nd generation 1,2,4-trioxane-ferrocene hybrids. In vitro tests against the CCRF-CEM leukemia cell line revealed di-1,2,4-trioxane-ferrocene hybrid 7 as the most active compound (IC50 of 0.01 μM). Regarding the activity against the multidrug resistant subline CEM/ADR5000, 1,2,4-trioxane-ferrocene hybrid 5 showed a remarkable activity (IC50 of 0.53 μM). Contrary to the antimalaria activity of hybrids 4–8 against Plasmodium falciparum …

Human cytomegalovirusMetallocenesPlasmodium falciparumHeterocyclic Compounds 4 or More RingsInhibitory Concentration 50chemistry.chemical_compoundHeterocyclic CompoundsCell Line TumorDrug DiscoverymedicineHumansFerrous CompoundsArtemisininIC50HybridPharmacologyLeukemiabiologyOrganic ChemistryPlasmodium falciparumGeneral Medicinebiology.organism_classificationmedicine.diseaseVirologyArtemisininsDrug Resistance MultipleMultiple drug resistanceBiochemistryFerrocenechemistry124-Trioxanemedicine.drugEuropean Journal of Medicinal Chemistry
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