Search results for "Potocki"

showing 5 items of 5 documents

Translocations Disrupting PHF21A in the Potocki-Shaffer-Syndrome Region Are Associated with Intellectual Disability and Craniofacial Anomalies

2012

Contains fulltext : 110038.pdf (Publisher’s version ) (Closed access) Potocki-Shaffer syndrome (PSS) is a contiguous gene disorder due to the interstitial deletion of band p11.2 of chromosome 11 and is characterized by multiple exostoses, parietal foramina, intellectual disability (ID), and craniofacial anomalies (CFAs). Despite the identification of individual genes responsible for multiple exostoses and parietal foramina in PSS, the identity of the gene(s) associated with the ID and CFA phenotypes has remained elusive. Through characterization of independent subjects with balanced translocations and supportive comparative deletion mapping of PSS subjects, we have uncovered evidence that t…

AdultMaleAdolescentGenotypePotocki–Shaffer syndromeChromosome DisordersHaploinsufficiencyBiologyHistone DeacetylasesSodium ChannelsTranslocation GeneticArticleChromatin remodelingCraniofacial Abnormalities03 medical and health sciencesSCN3A0302 clinical medicineIntellectual DisabilityNAV1.3 Voltage-Gated Sodium ChannelmedicineTranscriptional regulationGeneticsAnimalsHumansDeletion mappingGenetics(clinical)CraniofacialZebrafishGenetics (clinical)030304 developmental biologyGenetics0303 health sciencesChromosomes Human Pair 11Infant Newbornmedicine.diseaseGenetics and epigenetic pathways of disease DCN MP - Plasticity and memory [NCMLS 6]Child PreschoolHomeoboxFemaleChromosome DeletionHaploinsufficiencyExostoses Multiple Hereditary030217 neurology & neurosurgeryThe American Journal of Human Genetics
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Sapieżyńska ochrona dóbr Potockich w starostwie owruckim w latach 80. i 90. XVII wieku Przyczynek do badań nad współpracą rodzin magnackich w czasach…

2019

The Sapiehas and the Potockis were amongst the most influential families of the Polish‑Lithuanian Commonwealth. The latter family owned numerous estates in Ukraine, which were directly under threat from marching Lithuanian soldiers. Kazimierz Jan Sapieha, Grand Hetman of Lithuania was in charge of the said estates. Due to cooperation of the two magnate families, he attempted to shield the Potockis’ estates and possessions from Lithuanian troops marching to or returning from the war with Turkey. To that aim he utilised legal proclamations called Universals. The Potockis returned the favour by entering into political collaboration. Hetman Kazimierz Jan Sapieha, having been absent from the Sie…

Bajorai didikai ir magnatai / Nobles and magnatesUkraina (Ukraine)Sapiegos (Sapiega family)Lietuva (Lithuania)Dvarai / ManorsLenkija (Lenkijos karalystė; Rzeczpospolita Polska; Kingdom of Poland; Poland)Kariuomenė / ArmyŽemėvalda. Žemėtvarka / Land managementTurkija (Turkey)Potockiai (Potockis family)Abiejų Tautų Respublika (ATR; Rzeczpospolita Obojga Narodów; Žečpospolita; Sandrauga; Polish-Lithuanian Commonwealth; Lenkija ir Lietuva; Lenkijos ir Lietuvos Valstybė; Lenkijos-Lietuvos unija)
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New Insights into Potocki-Shaffer Syndrome: Report of Two Novel Cases and Literature Review

2020

Potocki-Shaffer syndrome (PSS) is a rare non-recurrent contiguous gene deletion syndrome involving chromosome 11p11.2. Current literature implies a minimal region with haploinsufficiency of three genes, ALX4 (parietal foramina), EXT2 (multiple exostoses), and PHF21A (craniofacial anomalies, and intellectual disability). The rest of the PSS phenotype is still not associated with a specific gene. We report a systematic review of the literature and included two novel cases. Because deletions are highly variable in size, we defined three groups of patients considering the PSS-genes involved. We found 23 full PSS cases (ALX4, EXT2, and PHF21A), 14 cases with EXT2-ALX4, and three with PHF21A only…

LSD-CoRESTPotocki–Shaffer syndromeReviewBioinformaticsSCNAlcsh:RC321-57103 medical and health sciences0302 clinical medicineEpileptic encephalopathy; Infantile spasms; Intellectual disability; LSD-CoREST; PHF21A; Potocki-Shaffer; SCNA; West syndromePotocki-ShafferIntellectual disabilityMedicineCraniofaciallcsh:Neurosciences. Biological psychiatry. Neuropsychiatry030304 developmental biology0303 health sciencesbusiness.industryGeneral NeuroscienceWest Syndromewest syndromemedicine.diseasePhenotypePHF21Astomatognathic diseasesEpileptic spasmsepileptic encephalopathySCNAintellectual disability<i>PHF21A</i>businessHaploinsufficiency030217 neurology & neurosurgeryinfantile spasmsBrain Sciences
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L'esthétique de la laideur dans le Manuscrit trouvé à Saragosse

2001

Il contributo si propone di mettere in evidenza l'estetica del brutto nel noto romanzo di Jan Potocki facendo uso delle categorie estetiche estrapolate dalla riflessione di Karl Rosenkranz.

LaideurSettore L-LIN/03 - Letteratura FrancesePotockiroman
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Sapieżyńska ochrona dóbr Potockich w starostwie owruckim w latach 80. i 90. XVII wieku: przyczynek do badań nad współpracą rodzin magnackich w czasac…

2019

Sapiehowie i Potoccy byli jednymi z najbardziej wpływowych rodzin w dawnej Rzeczypospolitej. Druga z wymienionych familii posiadała liczne dobra na Ukrainie, które rujnowały częste przemarsze żołnierzy litewskich. Władzę nad nimi sprawował hetman wielki Kazimierz Jan Sapieha. Zasadniczym celem artykułu jest rozpatrzenie kwestii dotyczącej możliwej ochrony przez hetmana Sapiehę dóbr Potockich w zamian za ich głosy poparcia na sejmie i obronę w czasie ataków na litewskiego dowódcę wywołanych jego absencją pod Wiedniem.

UkrainaSapiehasPotoccysoldiersSapiehowiemajątkiwojskoestates and possessionsPotockisUkraineWieki Stare i Nowe
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