Search results for "Developmental Disorder"

showing 10 items of 147 documents

Missense variants in DPYSL5 cause a neurodevelopmental disorder with corpus callosum agenesis and cerebellar abnormalities

2021

International audience; The collapsin response mediator protein (CRMP) family proteins are intracellular mediators of neurotrophic factors regulating neurite structure/spine formation and are essential for dendrite patterning and directional axonal pathfinding during brain developmental processes. Among this family, CRMP5/DPYSL5 plays a significant role in neuronal migration, axonal guidance, dendrite outgrowth, and synapse formation by interacting with microtubules. Here, we report the identification of missense mutations in DPYSL5 in nine individuals with brain malformations, including corpus callosum agenesis and/or posterior fossa abnormalities, associated with variable degrees of intel…

Models MolecularMale0301 basic medicineHydrolases[SDV]Life Sciences [q-bio]Hippocampal formationMedical and Health Sciences0302 clinical medicineNeurodevelopmental disorderTubulinModelsNeurotrophic factorsCerebellumIntellectual disability2.1 Biological and endogenous factorsMissense mutationAetiologyChilddendrite branchingGenetics (clinical)de novo missense variantsPediatricGenetics & HeredityDPYSL5Biological Sciences[SDV] Life Sciences [q-bio]corpus callosum agenesisMental HealthChild PreschoolNeurologicalFemaleMicrotubule-Associated ProteinsAdultNeuriteIntellectual and Developmental Disabilities (IDD)primary neuronal culturesMutation MissenseBiologyYoung Adult03 medical and health sciencesRare DiseasesMediatorReportIntellectual DisabilityGeneticsmedicineHumansPreschoolCorpus Callosum Agenesisbrain malformationNeurosciencesMolecularmedicine.diseaseneurodevelopmental disorderBrain Disorders030104 developmental biologyNeurodevelopmental DisordersMutationMissenseAgenesis of Corpus CallosumNeuroscience030217 neurology & neurosurgery
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Psychiatric genome-wide association study analyses implicate neuronal, immune and histone pathways

2015

G.B. and S.N. acknowledge funding support for this work from the National Institute for Health Research (NIHR) Mental Health Biomedical Research Centre at South London and Maudsley NHS Foundation Trust and King's College London. P.H.L. is supported by US National Institute of Mental Health (NIMH) grant K99MH101367. Genome-wide association studies (GWAS) of psychiatric disorders have identified multiple genetic associations with such disorders, but better methods are needed to derive the underlying biological mechanisms that these signals indicate. We sought to identify biological pathways in GWAS data from over 60,000 participants from the Psychiatric Genomics Consortium. We developed an an…

Netherlands Twin Register (NTR)Statistical methodsAutismMedizinLOCIGenome-wide association studyheritabilityGenome-wide association studiesHistonesGenètica mèdica0302 clinical medicineHistone methylationDatabases Genetic2.1 Biological and endogenous factorsPsychologyGWASAetiologyPsychiatric geneticsR2Cbipolar disorderPsychiatry0303 health sciencesDisordersLociDepressionGeneral NeuroscienceMental DisordersMedical geneticsMETHYLATIONBrain3rd-DASSerious Mental IllnessPsychiatric Disorders3. Good healthHistoneMental HealthSchizophreniaMental DisorderCognitive Sciences[SDV.NEU]Life Sciences [q-bio]/Neurons and Cognition [q-bio.NC]PromotersBDCBURDENRC0321 Neuroscience. Biological psychiatry. NeuropsychiatryHumanSignal Transductionmedicine.medical_specialtyDISORDERSGenomicsNetwork and Pathway Analysis Subgroup of Psychiatric Genomics ConsortiumBurdenBiologyMethylationArticleBiological pathwayPROMOTERS03 medical and health sciencesDatabasesGeneticmedicineGenetics/dk/atira/pure/keywords/cohort_studies/netherlands_twin_register_ntr_HumansGenetic Predisposition to Diseasehistone methylationBipolar disorderPsiquiatriaAUTISMPsychiatry030304 developmental biologyGenetic associationNeurodevelopmental disorders Donders Center for Medical Neuroscience [Radboudumc 7]Neurology & NeurosurgeryNeuroscience (all)Human GenomeNeurosciencesmedicine.diseaseBrain DisordersGood Health and Well BeingDE-NOVO MUTATIONSPerturbações do Desenvolvimento Infantil e Saúde MentalRC0321SchizophreniaGenome-wide Association StudiesDe-novo mutationsmajor depressionNeuroscience030217 neurology & neurosurgeryGenome-Wide Association Study
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A minireview about preterm birth and main specific neurodevelopmental disorders

2018

The preterm birth interrupts the physiological processes that allow the development of the Nervous System and of the body apparatus. Preterm children present a multi-organ dysfunction inversely proportional to the gestational age, leading to respiratory, cardiovascular, haematological, metabolic, infectious, and neurological problems.

Neurodevelopmental disorderSensorial disabilityMedicine (all)Specific learning disorderVery low birth weight
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Genome-wide analyses of individual differences in quantitatively assessed reading- and language-related skills in up to 34,000 people

2022

Published August 23, 2022 The use of spoken and written language is a fundamental human capacity. Individual differences in reading- and language-related skills are influenced by genetic variation, with twin-based heritability estimates of 30 to 80% depending on the trait. The genetic architecture is complex, heterogeneous, and multifactorial, but investigations of contributions of single-nucleotide polymorphisms (SNPs) were thus far underpowered. We present a multicohort genome-wide association study (GWAS) of five traits assessed individually using psychometric measures (word reading, nonword reading, spelling, phoneme awareness, and nonword repetition) in samples of 13,633 to 33,959 part…

NeuroinformaticsAdultkieli ja kieletAdolescentIndividualityQH426 GeneticsPolymorphism Single NucleotidelukeminenLanguage in InteractionYoung AdultSDG 3 - Good Health and Well-beingRA0421readingRA0421 Public health. Hygiene. Preventive MedicineHumansSpeechstudyPolymorphismReading jPreschoolChildQH426perinnöllisyysGenome-wide Association Study ; Language ; Meta-analysis ; ReadingLanguageMCCNeurodevelopmental disorders Donders Center for Medical Neuroscience [Radboudumc 7]genome-wide association studylanguageMultidisciplinarymeta-analyysi1184 Genetics developmental biology physiologykielitaito[SDV.NEU.SC]Life Sciences [q-bio]/Neurons and Cognition [q-bio.NC]/Cognitive SciencesDASSingle Nucleotide/dk/atira/pure/sustainabledevelopmentgoals/quality_educationmeta-analysisReadingGenetic LociChild Preschoolgenome-wide association study; language; meta-analysis; reading; Adolescent; Adult; Child; Child Preschool; Genetic Loci; Humans; Language; Polymorphism Single Nucleotide; Young Adult; Genome-Wide Association Study; Individuality; Reading; Speechperimälukutaitogenome-wide associationSDG 4 - Quality EducationGenome-Wide Association StudyProceedings of the National Academy of Sciences
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Oral, facial, digital, vertebral anomalies with psychomotor delay: a mild form of OFD type Gabrielli?

2002

A girl with oral, facial, and digital anomalies presented at birth with a large cleft palate filled by a nasopharyngeal mass and was found later to have several vertebral anomalies and mental retardation. A similar phenotype has been previously reported in a sporadic male patient [Gabrielli et al., 1994: Am J Med Genet 53:290-293], suggesting a new variant form of oral-facial-digital syndrome.

Oral facial digitalVertebral anomaliesOFD syndromemedicineHumansAbnormalities MultipleMild formGenetics (clinical)cleft palatebusiness.industryhairy polypInfant NewbornBrainInfantAnatomyOFD syndrome; cleft palate; hairy polyp; vertebral anomalies; occipital anomaliesNew variantvertebral anomaliesmedicine.diseaseoccipital anomaliesVertebraDevelopmental disorderstomatognathic diseasesmedicine.anatomical_structureEl NiñoFemalePsychomotor DisordersbusinessTomography X-Ray ComputedPsychomotor delayNeckAmerican journal of medical genetics
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Benign nocturnal alternating hemiplegia of childhood: a new case with unusual findings

2014

Abstract It has been described a neuro developmental disorder labelled “Benign nocturnal alternating hemiplegia of childhood” (BNAHC) characterized by recurrent attacks of nocturnal hemiplegia without progression to neurological or intellectual impairment. We report a female patient who at 11 months revealed a motionless left arm, unusual crying without impairment of consciousness and obvious precipitating factors. The attacks occur during sleep in the early morning with lack of ictal and interictal electroencephalographic abnormalities, progressive neurological deficit, and cognitive impairment. Unlike previous reports of BNAHC our patient come from a family with a history of both migraine…

Pediatricsmedicine.medical_specialtyHemiplegiaNocturnalHemiplegic migraineDiagnosis DifferentialDevelopmental NeuroscienceSettore M-PSI/08 - Psicologia ClinicamedicineHumansIctalFamilyBenign nocturnal alternating hemiplegia of childhood; Alternating hemiplegia of childhood; Hemiplegic migraine; Sleep disordersSettore M-PSI/02 - Psicobiologia E Psicologia FisiologicaCryingIntellectual impairmentAlternating hemiplegia of childhoodSleep disordersGeneral Medicinemedicine.diseaseSettore MED/39 - Neuropsichiatria InfantileDevelopmental disorderMigraineAlternating hemiplegia of childhoodChild PreschoolPediatrics Perinatology and Child HealthHemiplegic migrainePhysical therapyFemaleNeurology (clinical)medicine.symptomPsychologySleepBenign nocturnal alternating hemiplegia of childhood
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Efficiency of Multisensoric Therapy in Autism Spectrum Disorder Patients

2018

Abstract The aim of this study was to investigate the role of various treatment methods for children with autistic spectrum disorders (ASD). The prospective study was conducted in 2013–2015 at the Children’s University Hospital and Social Pediatric Centre of the University of Latvia. The data analysis included 72 children (2 to 5 year old) with ASD, of whom 38 had infantile autism, 16 had atypical autism, and 18 had other diffuse developmental disorder). 86.1% patients received therapy. The most common treatment was by Montessori method and special pedagogue. Other treatments were dance-movement therapy, animal, sand and one patient received spa treatments. Univariate OR analysis showed tha…

Pediatricsmedicine.medical_specialtyMultidisciplinarypsychomotor developmentScienceQTreatment methodautismmultisensory therapymedicine.diseaseUniversity hospitalSpecial educationDevelopmental disordermontessori methodAutism spectrum disordermedicineAutismMontessori methodProspective cohort studyProceedings of the Latvian Academy of Sciences. Section B, Natural Sciences
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Early patterns of electrical activity in the developing cerebral cortex of humans and rodents.

2006

International audience; During prenatal and early postnatal development, the cerebral cortex exhibits synchronized oscillatory network activity that is believed to be essential for the generation of neuronal cortical circuits. The nature and functional role of these early activity patterns are of central interest in neuroscience. Much of the research is performed in rodents and in vitro, but how closely do these model systems relate to the human fetal brain? In this review, we compare observations in humans with in vivo and in vitro rodent data, focusing on particular oscillatory activity patterns that share many common features: delta brushes, spindle bursts and spindle-like oscillations. …

PeriodicityMESH: PeriodicityRodentPeriod (gene)Central nervous systemModels NeurologicalMESH: NeuronsNeurological disorder[SDV.BC]Life Sciences [q-bio]/Cellular Biology03 medical and health sciences0302 clinical medicineMESH: Models Neurologicalbiology.animalmedicineAnimalsHumansMESH: Animals[SDV.BC] Life Sciences [q-bio]/Cellular Biology030304 developmental biologyCerebral CortexNeurons0303 health sciencesMESH: HumansbiologyGeneral Neurosciencemedicine.diseaseMESH: Cerebral CortexDevelopmental disorderElectrophysiologymedicine.anatomical_structureMESH: Nerve NetCerebral cortexHuman fetalNerve NetPsychologyNeuroscience030217 neurology & neurosurgery
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The quality of life of children with pervasive developmental disorders

2009

AIM: Quality of life is increasingly the focus of attention by health, psychological and social services. Pervasive developmental disorders (PDD) are a group of psychiatric conditions in which the patient's clinical case history is characterized by disturbances in social interaction, deterioration of verbal and non-verbal communication, and presence of bizarre, limited and stereotyped activity. These disturbances affect multiple developmental areas and show up in very early stages of development, resulting in a permanent disorder. Many studies have sought to recognize causes and interventions for persons with PDD, however, they often take insufficient account of the effects these disorder c…

Pervasive Developmental Disorders Quality of life Age developmentSettore MED/39 - Neuropsichiatria Infantile
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Urinaryp-cresol is elevated in young French children with autism spectrum disorder: a replication study

2014

The aromatic compound p-cresol (4-methylphenol) has been found elevated in the urines of Italian autistic children up to 8 years of age. The present study aims at replicating these initial findings in an ethnically distinct sample and at extending them by measuring also the three components of urinary p-cresol, namely p-cresylsulfate, p-cresylglucuronate and free p-cresol. Total urinary p-cresol, p-cresylsulfate and p-cresylglucuronate were significantly elevated in 33 French autism spectrum disorder (ASD) cases compared with 33 sex- and age-matched controls (p < 0.05). This increase was limited to ASD children aged ≤8 years (p < 0.01), and not older (p = 0.17). Urinary levels of p-cresol a…

Pervasive developmental disordersMalePathologyHealth Toxicology and MutagenesisClinical BiochemistryBiochemistryClinical biochemistryCresolsorganic contaminants; neurotoxicity; Gut flora; pervasive developmental disorders; p-cresylsulfateUrinary levelsneurotoxicityChildSettore BIO/12P-cresylsulfateSettore MED/39 - Neuropsichiatria InfantileGut flora neurotoxicity organic contaminants p-cresylsulfate pervasive developmental disordersHealthAutism spectrum disorderChild Preschoolp-cresylsulfateBiomarker (medicine)FemaleFrancemedicine.medical_specialtyChild Development DisordersAdolescentUrinary systemGlucuronatesSulfuric Acid EstersOrganic contaminantsGut flora; Neurotoxicity; Organic contaminants; p-cresylsulfate; Pervasive developmental disorders; Adolescent; Case-Control Studies; Child; Child Development Disorders; Pervasive; Child; Preschool; Cresols; Female; France; Glucuronates; Humans; Male; Sulfuric Acid Esters; Biochemistry; Clinical Biochemistry; Health; Toxicology and MutagenesisInternal medicineparasitic diseasesNeurotoxicitymedicineHumansToxicology and MutagenesisPreschoolSettore BIO/10 - BIOCHIMICAPervasiveGut florabusiness.industryCase-control studypervasive developmental disordersmedicine.diseaseChild Development Disorders PervasiveCase-Control StudiesAutismorganic contaminantsGut flora; Neurotoxicity; Organic contaminants; p-cresylsulfate; Pervasive developmental disorders; Adolescent; Case-Control Studies; Child; Child Development Disorders Pervasive; Child Preschool; Cresols; Female; France; Glucuronates; Humans; Male; Sulfuric Acid Esters; Biochemistry; Clinical Biochemistry; Health Toxicology and MutagenesisbusinessBiomarkers
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