Search results for "complex"

showing 10 items of 5889 documents

Functional Assessment of Variants in the TSC1 and TSC2 Genes Identified in Individuals with Tuberous Sclerosis Complex

2011

The effects of missense changes and small in-frame deletions and insertions on protein function are not easy to predict, and the identification of such variants in individuals at risk of a genetic disease can complicate genetic counselling. One option is to perform functional tests to assess whether the variants affect protein function. We have used this strategy to characterize variants identified in the TSC1 and TSC2 genes in individuals with, or suspected of having, Tuberous Sclerosis Complex (TSC). Here we present an overview of our functional studies on 45 TSC1 and 107 TSC2 variants. Using a standardized protocol we classified 16 TSC1 variants and 70 TSC2 variants as pathogenic. In add…

congenital hereditary and neonatal diseases and abnormalitiesGenetic counselingtuberous sclerosis complexBiologyTuberous Sclerosis Complex 1 Protein03 medical and health sciencesTuberous sclerosis0302 clinical medicineTuberous SclerosisGenetic variationTuberous Sclerosis Complex 2 ProteinGeneticsmedicineMissense mutationHumansunclassified variantsGeneGenetics (clinical)Cells Cultured030304 developmental biologyGenetics0303 health sciencesModels GeneticTumor Suppressor ProteinsLife SciencesGenetic Variationmedicine.diseaseTSC23. Good healthnervous system diseasesTSC1medicine.anatomical_structureTSC1TSC2030217 neurology & neurosurgeryCommon disease-common variant
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Huntingtin controls neurotrophic support and survival of neurons by enhancing BDNF vesicular transport along microtubules.

2004

AbstractPolyglutamine expansion (polyQ) in the protein huntingtin is pathogenic and responsible for the neuronal toxicity associated with Huntington's disease (HD). Although wild-type huntingtin possesses antiapoptotic properties, the relationship between the neuroprotective functions of huntingtin and pathogenesis of HD remains unclear. Here, we show that huntingtin specifically enhances vesicular transport of brain-derived neurotrophic factor (BDNF) along microtubules. Huntingtin-mediated transport involves huntingtin-associated protein-1 (HAP1) and the p150Glued subunit of dynactin, an essential component of molecular motors. BDNF transport is attenuated both in the disease context and b…

congenital hereditary and neonatal diseases and abnormalitiesHuntingtinCell SurvivalContext (language use)Nerve Tissue ProteinsMicrotubulesModels BiologicalGeneral Biochemistry Genetics and Molecular BiologyMiceNeurotrophic factorsmental disordersHuntingtin ProteinAnimalsCells CulturedNeuronsHuntingtin ProteinbiologyBiochemistry Genetics and Molecular Biology(all)Huntingtin-associated protein 1Brain-Derived Neurotrophic FactorCytoplasmic VesiclesBrainNuclear ProteinsBiological TransportDynactin ComplexCell biologynervous system diseasesVesicular transport proteinDNA-Binding ProteinsBiochemistrynervous systembiology.proteinDynactinMicrotubule-Associated ProteinsNeurotrophinCell
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Methionine in a protein hydrophobic core drives tight interactions required for assembly of spider silk

2019

Web spiders connect silk proteins, so-called spidroins, into fibers of extraordinary toughness. The spidroin N-terminal domain (NTD) plays a pivotal role in this process: it polymerizes spidroins through a complex mechanism of dimerization. Here we analyze sequences of spidroin NTDs and find an unusually high content of the amino acid methionine. We simultaneously mutate all methionines present in the hydrophobic core of a spidroin NTD from a nursery web spider’s dragline silk to leucine. The mutated NTD is strongly stabilized and folds at the theoretical speed limit. The structure of the mutant is preserved, yet its ability to dimerize is substantially impaired. We find that side chains of…

congenital hereditary and neonatal diseases and abnormalitiesProtein Foldinggenetic structuresProtein ConformationScienceSilkmacromolecular substancesCircular dichroismcomplex mixturesArticleMethionineddc:590ddc:570AnimalsAmino Acid Sequencelcsh:ScienceFluorescence spectroscopySequence Homology Amino AcidfungiQtechnology industry and agricultureSpidersSpectrometry FluorescenceMutationThermodynamicslcsh:QProtein MultimerizationFibroinsSolution-state NMRHydrophobic and Hydrophilic InteractionsAlgorithmsNature Communications
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Variation and variability in L2 learning trajectories : Learning the Finnish existential construction

2022

Taking an onomasiological approach and a dynamic usage-based perspective, this study explores how four beginning L2 learners of Finnish develop in expressing existentiality (‘there is something somewhere’) before and after instruction. Data were collected weekly over a period of nine months and examined for conventionalized and non-conventionalized constructions that express existentiality. As expected from a dynamic usage-based perspective, both inter-individual variation and intra-individual variability were identified. The initial repertoires of two of the learners were quite variable, as they used several different non-conventionalized constructions before settling on more conventionali…

constructionusage-based linguisticssuomen kieliL2 FinnishL2 developmentsysteemiteoriasuomi toisena kielenäkielen oppiminencomplex dynamic systems theorykonstruktiokielioppi
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Incorporation of Pt(II) complex with [amino-2(methylthio)(1,2,4)triazole-(1,5-a)pyrimidine-6-carboxylic-acid] ligand in MCM41 for controlled release

2015

Drug carriers play a critical role for the loading and the release of the drug. A promising frontier is represented by a new class of innovative medicines that represents directional transport vehicles "drug delivery" and consist of assembled structures carrier (nano)-drug. Silica-based materials, nontoxic, biocompatible, have been used as adjuvant and excipient in pharmaceutical technology. In this class of compounds, the mesoporous materials, such as MCM41, SBA-15 and hexagonal mesoporous silica, have been investigated for medication and drug delivery due to their properties. In fact, these materials show a large specific pore volume made up of regular pores having a diameter in the nanom…

controlled release MCM41 platinum(II) complexes 29Si {1H} CP-MAS NMR.
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Application of Silsesquioxanes in the Preparation of Polyolefin-Based Materials

2023

This paper is a review of studies on the use of the polyhedral oligomeric silsesquioxanes (POSS) of various structures in the synthesis of polyolefins and the modification of their properties, namely: (1) components of organometallic catalytic systems for the polymerization of olefins, (2) comonomers in the copolymerization with ethylene, and (3) fillers in composites based on polyolefins. In addition, studies on the use of new silicon compounds, i.e., siloxane–silsesquioxane resins, as fillers for composites based on polyolefins are presented. The authors dedicate this paper to Professor Bogdan Marciniec on the occasion of his jubilee.

copolymerizationPOSS-comonomersiloxane–silsesquioxane resinpolymerizationtransition metal–silsesquioxane complexcompositepolyolefinsolefinPOSScatalystMaterials
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Probing the origin of ultra-high-energy cosmic rays with neutrinos in the EeV energy range using the Pierre Auger Observatory

2019

Neutrinos with energies above 1017 eV are detectable with the Surface Detector Array of the Pierre Auger Observatory. The identification is efficiently performed for neutrinos of all flavors interacting in the atmosphere at large zenith angles, as well as for Earth-skimming τ neutrinos with nearly tangential trajectories relative to the Earth. No neutrino candidates were found in ∼ 14.7 years of data taken up to 31 August 2018. This leads to restrictive upper bounds on their flux. The 90% C.L. single-flavor limit to the diffuse flux of ultra-high-energy neutrinos with an Eν -2 spectrum in the energy range 1.0 × 1017 eV -2.5 × 1019 eV is E2 dNν/dEν < 4.4 × 10-9 GeV cm-2 s-1 sr-1, placing str…

cosmological neutrinosAstronomyFluxAstrophysics01 natural sciences7. Clean energycosmic ray experiments; cosmological neutrinos; neutrino astronomy; ultra high energy cosmic rayssurface [detector]Ultra-high-energy cosmic rayPhysicsHigh Energy Astrophysical Phenomena (astro-ph.HE)cosmological neutrinoSettore FIS/01 - Fisica SperimentaleDETETORESneutrino: UHEUHE [neutrino]Augerobservatorytrajectoryneutrino: flavorProduction (computer science)NeutrinoAstrophysics - High Energy Astrophysical PhenomenaAstrophysics::High Energy Astrophysical PhenomenaUHE [cosmic radiation]FOS: Physical sciencescosmic ray experimentCosmic rayultra high energy cosmic raysneutrino: productionneutrino astronomyproduction [neutrino]TheoryofComputation_ANALYSISOFALGORITHMSANDPROBLEMCOMPLEXITY0103 physical sciencesddc:530model [neutrino]High Energy Physicscosmic radiation: UHEZenithAstrophysiqueneutrino: modelPierre Auger ObservatorySPECTRUM010308 nuclear & particles physicsdetector: surfaceHigh Energy Physics::Phenomenologyflavor [neutrino]Astronomy and AstrophysicsAstronomiefluxExperimental High Energy PhysicsatmosphereHigh Energy Physics::Experimentcosmic ray experiments[PHYS.ASTR]Physics [physics]/Astrophysics [astro-ph]Energy (signal processing)
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Species size affects hatching response to different temperature regimes in a rotifer cryptic species complex

2013

The strategy of decreasing size with increasing temperature known as Bergmann’s rule operates at geographic scale and in spite of extensive studies still presents a puzzle to researches. The aim of this work was to verify whether patterns of diapausing egg hatching of closely related species are consistent with the expectations from Bergmann’s rule. In a laboratory study of the cryptic species complex of the rotifer Brachionus plicatilis, the response to temperature (17.5, 22.5, and 25.0 °C) of diapausing eggs collected in a pond where the three tested species coexist was assessed by (1) the number of hatchlings emerging or (2) the time needed to hatch. Our results show that the response to…

cryptic speciesSpecies complexbiologyEcologyHatchingBergmann’s ruleRotiferadaptationBrachionusDiapausebiology.organism_classificationresting eggsBergmann's ruleAnimal ecologyembryonic structuresbody sizeegg bankHatchlingEcology Evolution Behavior and SystematicsEvolutionary Ecology
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Catena-poly[[di-n-butyltin(IV)]-mu-trifluoromethanesulfonato-[[di-n-butyl(trifluoromethanesulfonato)tin(IV)]-di-mu-hydroxo]]

2006

International audience

crystal structure010405 organic chemistryChemistrycatena complexGeneral Chemistry[CHIM.INOR]Chemical Sciences/Inorganic chemistry010402 general chemistryCondensed Matter Physics01 natural sciencesMedicinal chemistry0104 chemical sciences3. Good healthtinGeneral Materials ScienceComputingMilieux_MISCELLANEOUS
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The first copper(I)-olefin complexes bearing a 1,3,4-oxadiazole core: Alternating-current electrochemical crystallization, X-ray experiment and DFT s…

2017

By means of alternating-current electrochemical technique, four new π-complexes, namely [Cu2(C11H10N2OS)2Br1.91Cl0.09] (1), [Cu(C11H10N2OS)NO3] (2), [Cu2(C11H10N2OS)2(H2O)2](BF4)2 (3) and [Cu2(C11H10N2OS)2(H2O)2](ClO4)2 (4), were obtained using copper(II) salts and the 2-(allylthio)-5-phenyl-1,3,4-oxadiazole (C11H10N2OS) ligand. The metal and halogen centers in 1 form Cu2X2 dimers; the N-atom from the oxadiazole ring and the Cdouble bond; length as m-dashC bond of the allyl group from the same ligand complete the copper coordination environment, giving [Cu(C11H10N2OS)X]2 isolated fragments. The ligand plays the same chelating role in 2, whereas the O (NO3) atom occupies the third position i…

crystal structure3Stereochemistry1chemistry.chemical_elementOxadiazolekupariCrystal structure134-oxadiazole derivatives4-oxadiazole derivatives010402 general chemistryElectrochemistryRing (chemistry)DFT01 natural sciencesolefinpi-complexInorganic ChemistryMetalchemistry.chemical_compoundraman spectroscopyMaterials ChemistryMoleculePhysical and Theoretical Chemistryta116010405 organic chemistryLigandac-electrochemical techniquekompleksiyhdisteetCoppercopper(I)0104 chemical sciencesCrystallographychemistryvisual_artvisual_art.visual_art_mediumPolyhedron
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